A Little Person With A Giant Umbilical Cord | |
Woo Sze Yao 1* and Koay Yen Wee 2 | |
1Department Of General Surgery, University Kebangsaan Malaysia, Kuala Lumpur, Malaysia | |
2 DepartmentOf Peadiatric Surgery, Hospital Tunku Azizah, Kuala Lumpur, Malaysia | |
* Correspondence author: Woo Sze Yao; garyltdwork@gmail.com | |
ISSN: 2754-8880 | |
Published 00 11 0000 | |
ORIGINAL | |
Abstract | |
The giant umbilical cord is a rare anomaly that is usually detected in the antenatal period and is | |
distinctive at birth. It is a condition where the diameter of the cord is more than 5 centimeters | |
in diameter. A normal umbilical cord measures approximately 2 centimeters in diameter. We | |
present a case of a giant umbilical cord in a male baby, in whom this condition was diagnosed | |
antenatally. At birth, its appearance is pathognomonic with a large, thickened cord filled with | |
viscid fluid called Wharton’s jelly. The umbilical vessels were apparent from the surface of the | |
cord. Surgical exploration which was done revealed no patent urachus. It is pertinent to rule out | |
other associated anomalies or differential diagnoses when encountering this condition. | |
Keywords : Umbilical anomaly, giant umbilical cord, umbilical pseudocyst | |
Introduction | |
The "belly button", ”navel" and "umbilicus". These are but different terms for that singular structure | |
seen at the center of the abdomen. It is essentially the first scar on the body, created by the | |
detachment of the umbilical cord soon after birth. | |
As simple as the detachment of the umbilical cord by the obstetrician or midwife as it may seem, | |
there are certain rare disorders of the umbilical cord which warrant a consultation by the paediatric | |
surgeon. Among them is the giant umbilical cord (GUC). As the name implies, the giant umbilical | |
cord is defined as an enlargement of more than 5 cm in diameter of the cross-section of the | |
umbilical cord during the second trimester and beyond (1). We hereby would like to present a | |
rare case of a giant umbilical cord in an otherwise healthy baby boy. | |
Case Report | |
A male infant with a good birth weight of 2.55 kg was born via ELLSCS (elective lower section | |
Caesarean section) at 35 weeks and 4-days in view of an antenatally diagnosed giant umbilical | |
cord and placenta praevia posterior major. The birth process was uneventful. Postnatally the | |
child was nursed in the NICU (Neonatal Intensive Care Unit) for respiratory distress syndrome, a | |
common problem in premature newborns. At birth, the umbilical cord was detached at an area | |
where it appeared to have sufficiently tapered in diameter to prevent slippage of the cord clamp | |
OPEN ACCESS | (approximately 30 cm from its attachment to the umbilicus). |
Edited by | |
A.Hussain | This condition was first apparent during the antenatal scan at 26 weeks of gestational age |
Submitted 21 Aug. 2022 | undertaken by the 23 years old Gravida 1 Para 1(G1P1) mother. Subsequent serial scans were |
performed. These scans revealed an echogenic mass surrounding the umbilical arteries measuring | |
Accepted 23 Aug. 2022 | 3 x 0.6cm with cystic dilatation of the umbilical cord. Doppler scan showed normal flow through |
Citation | the umbilical vessels. A detailed scan showed no other structural abnormality. |
Woo Sze Yao, Koay Yen Wee. | |
A Little Person With A Giant | The decision for an elective birth was made in view of umbilical cord abnormality with placenta |
Umbilical Cord. | praevia major posterior. After birth, the infant was referred to the paediatric surgeon for further |
:BJOSS::2022:(3);86-90 |
evaluation and management. On examination, the child was active, pink, and had no dysmorphic |
features with normal vitals. Per abdomen examination revealed a soft, non-distended abdomen, |
no organomegaly, and an intact lower urinary tract. There was a firm mass about 4 x 4 cm at the |
foetal end of the cord upon examination of the umbilical cord. All 3-vessels (2 umbilical arteries |
and 1 umbilical vein) were seen within the thickened cord which contained a large amount of |
viscid fluid called Wharton’s jelly giving rise to a mucilaginous-like feel to the palpating fingers. |
Urachal remnants or a patent urachus weren’t visible to the naked eye. |
Surgical exploration of the giant umbilical cord and umbilicoplasty was done the next day. The |
peri-operative period was uneventful. The patient tolerated the operative procedure well. 2 |
umbilical arteries, 1 vein, and an obliterated umbilical remnant were identified. A bulky mass |
was seen in the proximal cord (correlated with the echogenic mass on antenatal scan and a firm |
mass palpable during examination) but there was no intraperitoneal extension. The fluid from |
the umbilical cord was collected and sent to the laboratory for biochemistry and FEME (full |
examination and microscopic examination) while the bulky mass was sent for histopathological |
examination. The returned laboratory results were unremarkable. |
Post-operatively, the patient recovered well. There was no discharge from the umbilical stump. |
The patient was discharged well on day 4-post-operation. The desiccated stump eventually fell off from the umbilical base. |
Figure 1. Giant umbilical cord. Note the visible umbilical vessels |
Figure 2. Intraoperative photo of the dissected umbilical cord with 2 umbilical arteries, 1 |
umbilical vein and an obliterated urachal remnant |
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Figure 3. The umbilicus at 1 month post-operation |
Discussion |
Incidence |
The giant umbilical cord is a rare disorder. Very few cases of GUC have been reported in the |
literature (1). An entensive literature search of medical journals using the keywords "umbilical |
anomaly", "giant umbilical cord", and "umbilical pseudocyst" only revealed 12 cases of GUC. |
Conversely, there are many reported cases of "large umbilical cords". These cases, however, do |
not satisfy the criteria for GUC as the size of the cords although are more than 2 cm but are less |
than 5 cm in diameter. |
Cord Facts |
The normal cord measures about 2cm in diameter (2) and 50-60 cm in length (3). Upon ultrasonog- |
raphy, the umbilical cord is visualised as an echogenic vine-like structure that forms a conduit |
between the foetus and the placenta (3). By 8 weeks of gestation, it is well visualised (3). The |
pathophysiology behind the giant umbilical cord isn’t well established but it has been posited that |
the existence of an osmotic gradient pulls the refluxed foetal urine towards the Wharton’s jelly, |
resulting in its swelling (4). |
Diagnosis |
Since the use of ultrasonography is ubiquitous during the antenatal period and is easily visualised, |
most cases of GUC, albeit rare, are diagnosed during this period. Though a rare occurrence itself, |
it is frequently associated with vascular or urachal anomalies (5). Male babies are twice more |
at risk to have urachal anomalies compared to females (6). A patent urachus in a GUC can be |
diagnosed by demonstrating a connection between the foetal bladder and the umbilical cord (7). |
Differential diagnosis |
There are various other aetiologies for a thickened oedematous umbilical cord e.g. omphalome- |
senteric duct remnants, umbilical bladder exstrophy, umbilical hernia, umbilical cord pseudocysts, |
or abdominal wall malformations (8). |
Management |
Almost all cases of GUC would require a surgical exploration of the umbilical cord as the patent |
urachus may not be evident on the antenatal ultrasound. In 2005, Wildhaber (7) reported a |
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case of a child who presented with a discharge of urine from the umbilicus 1 week after cord | |
clamping of the giant umbilical cord. This underpinned the importance of surgical exploration as | |
the post-natal ultrasonography may be inconclusive. | |
However, currently, opinion is divided as to whether a post-natal abdominal ultrasound and/ or | |
cysto-urography is necessary before embarking on the operation. In our case, we embarked on | |
the surgery without post-natal imaging. According to Young et al (9), GUCs with the absence | |
of urinary tract abnormalities during the antenatal scan do not require any investigations in the | |
newborn period. | |
One may argue that conservative management of GUC is theoretically possible in the absence | |
of evidence of a congenital patent urachus which by itself is a very rare condition occurring in | |
1-2.5 per 100 000 deliveries (10). A study by Stopak et al observed a complication rate of 18% | |
post surgery for urachal anomalies (urachal cyst, urachal sinus, or patent urachus) (11). In the | |
same study, about 87% of patients with urachal remnants who were treated conservatively had a | |
complete resolution within 1 year. Therefore it is recommended that with the high complication | |
rate (wound infection, persistent drainage, granuloma, or stitch abscess) and with the possibility of | |
spontaneous resolution, most urachal anomalies can be treated conservatively up to the first year | |
of life. There is a paucity of data regarding the incidence of GUCs, let alone that of conservative | |
vs surgical treatment for GUCs. Despite these limitations, most authors recommend surgical | |
exploration in the case of GUC. | |
Conclusion | |
To conclude, cases of GUC are very few and far in between. However if one is fortunate enough | |
to come across one, other anomalies associated with it, especially a patent urachus should be | |
ruled out. Surgical exploration is necessary for resection of the patent urachus in case it was | |
missed during ultrasonography. | |
Conflict Of Interest | |
All authors declare no conflict of interest of any kind. | |
References | |
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